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Gene under study

Gene PRRT2 (OMIM *614386) 

Abstract

Heterozygous PRRT2 variants are well-known causes of various paroxysmal disorders, such as paroxysmal kinesigenic dyskinesia (PKD), benign familial infantile epilepsy, hemiplegic migraine, and episodic ataxia (EA). In contrast, the evidence on autosomal recessive PRRT2-related disorders is more limited. 
Bi-allelic PRRT2 variants are linked to more severe disease phenotypes compared to the autosomal dominant form and are estimated to account for <1% of cases of PRRT2 related disorder. These more severe phenotypes include non-syndromic intellectual disability, persistent PKD attacks, autism spectrum disorder, attention-deficit hyperactivity disorder, various seizure types, migraine, paroxysmal non-kinesigenic dyskinesia, or EA.  
Our goal is to conduct a comprehensive phenotypic analysis and define the natural history of disorders associated with bi-allelic PRRT2 variants in a large, international cohort of patients. 

Coordinating clinician

Dr Francesca Magrinelli – f.magrinelli@ucl.ac.uk

Institution

Department of Clinical and Movement Neurosciences, UCL Queen Square Institute of Neurology, University College London, London, United Kingdom

Specific requirements beyond clinical data and genotype data sharing:

1- Re-analysis of DNA samples: Yes (not mandatory) 

2- Resampling of patients: Yes (not mandatory)

3- Linked to a translational/basic research project: No