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Targeted gene under study:

OMIM #618721

Abstract

Inborn deficiency of GOT2 (OMIM: 618721) due to biallelic missense variants was first reported in 2019 by van Karnebeek et al. in four children from three different families. These patients presented with early-onset developmental epileptic encephalopathy (DEE), accompanied by intellectual and motor delays. However, the clinical and genetic spectrum of this ultra-rare disorder remains largely uncharacterized.

To address this, we have been collecting clinical and genetic data from families affected by GOT2-related neurodevelopmental disorders with epilepsy. Additionally, we performed biochemical analyses on fibroblast cells and dried blood spot samples derived from the patients. We are currently preparing a manuscript reporting our findings from five new families, and it would be great to identify additional families to include before our first submission or during revision.

Coordinating team

Reza Maroofian – R.maroofian@ucl.ac.uk

Hannah M. German – H.M.German@umcutrecht.nl

Institutions

UCL Queen Square Institute of Neurology- department of neuromuscular disease

Section Metabolic Diagnostics, Department of Genetics, University Medical Centre Utrecht, Utrecht University, 3584 EA Utrecht, the Netherlands

Specific requirements beyond clinical data and genotype data sharing:

1- Re-analysis of DNA samples: No

2- Resampling of patients: Yes – Dried blood spots if this is possible

3- Linked to a translational/basic research project: Yes